Bài báo khoa học Tập 67 Số English Version No 1, 2026 02/06/2026

CLINICAL CHARACTERISTICS IN FEMALE CHILDREN WITH CONGENITAL ADRENAL HYPERPLASIA DUE TO 21-HYDROXYLASE DEFICIENCY UNDERGOING GENITAL RECONSTRUCTION SURGERY

Nguyen Thi Mai Thuy1, Duong Hong Van1, Tran Ngoc Nhat1
1 Department of Urological Surgery, National Children’s Hospital
DOI: 10.52163/yhc.v67iE1.5282
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Tóm tắt

Objective: To describe some clinical characteristics of female children with congenital adrenal hyperplasia (CAH) due to 21-hydroxylase deficiency who underwent feminizing genitoplasty. Subjects and Methods: A retrospective descriptive study was conducted on 103 female patients with CAH due to 21-hydroxylase deficiency who underwent feminizing external genital reconstruction performed by the same surgeon between 2020 and 2025 at the National Children’s Hospital.

Results: From January 2020 to December 2025, 103 female patients with CAH due to 21hydroxylase deficiency underwent feminizing external genital reconstruction by the same surgeon. 72% of patients were diagnosed during the neonatal period, predominantly presenting with the salt-wasting form. The simple virilizing form accounted for 28% of cases. The disease showed familial occurrence, with nearly one-quarter of patients having affected siblings. The mean age at surgery was 37 ± 35 months (range: 6–211 months). External genital abnormalities classified as Prader stages 2 and 3 were most common, accounting for 65% of cases. Severe forms with a high urogenital sinus (Prader stages 4 and 5) accounted for 25%.

Conclusion: In female children, CAH due to 21-hydroxylase deficiency most commonly presents as the salt-wasting form, is typically diagnosed in the neonatal period, and most frequently manifests with Prader stage 2 or 3 genital abnormalities.

Tài liệu tham khảo
[1]
Ibrahim H, Lachkar AA, Bidault V, Delcour C, Paye-Jaouen A, Peycelon M, and El-Ghoneimi A. Genito-Urinary Reconstruction in Female Children With Congenital Adrenal Hyperplasia: Favorable Surgical Outcomes Can Be Achieved by Contemporary Techniques and a Dedicated Multidisciplinary Management. Journal of Pediatric Surgery 2024 Sep; 59:1851– Google Scholar
[2]
DOI: 10.1016/j.jpedsurg.2024.05.009 Google Scholar
[3]
Sturm RM, Durbin-Johnson B, and Kurzrock EA. Congenital Adrenal Hyperplasia: Current Surgical Management at Academic Medical Centers in the United States. Journal of Google Scholar
[4]
Urology 2015 May; 193:1796–801. DOI: 10.1016/j.juro.2014.11.008 Google Scholar
[5]
Shalaby M, Chandran H, Elford S, Kirk J, and McCarthy L. Recommendations of Patients and Families of Girls with 46XX Congenital Adrenal Hyperplasia in the United Kingdom Regarding the Timing of Surgery. Pediatric Surgery International 2021 Jan; 37:137–43. Google Scholar
[6]
DOI: 10.1007/s00383-020-04780-3 Google Scholar
[7]
Kudela G, Gawlik A, and Koszutski T. Early Feminizing Genitoplasty in Girls with Congenital Adrenal Hyperplasia (CAH)—Analysis of Unified Surgical Management. International Journal of Environmental Research and Public Health 2020 May; 17:3852. DOI: Google Scholar
[8]
3390/ijerph17113852 Google Scholar
[9]
Abosena W, Almetaher HA, El Attar AA, Nofal AH, and Elhalaby EA. Outcomes of One-Stage Feminizing Genitoplasty in Children with Congenital Adrenal Hyperplasia and Severe Virilization. Pediatric Surgery International 2024 Mar; 40:72. DOI: 10.1007/ s00383-024-05638-8 Google Scholar
[10]
Zainuddin AA, Grover SR, Soon CH, Nur Azurah AG, Mahdy ZA, Wu LL, Rasat R, Harun F, Chia WY, and Shamsuddin K. Malaysian Females With Congenital Adrenal Hyperplasia: Surgical Outcomes and Attitudes. Frontiers in Pediatrics 2019 Apr; 7:144. DOI: 10.3389/ fped.2019.00144 Google Scholar
[11]
Fisher RS, Espeleta HC, Baskin LS, Buchanan CL, Chan YM, Cheng EY, Coplen DE, Diamond DA, Nokoff NJ, Palmer BW, Poppas DP, Scott Reyes KJ, Tishelman A, Wolfe- Google Scholar
[12]
Christensen C, Mullins LL, and Wisniewski AB. Decisional Regret about Surgical and NonSurgical Issues after Genitoplasty among Caregivers of Female Infants with CAH. Journal of Pediatric Urology 2022 Feb; 18:27–33. DOI: 10.1016/j.jpurol.2021.10.001 Google Scholar
[13]
Erginel B, Ozdemir B, Karadeniz M, Poyrazoglu S, Keskin E, and Soysal FG. Long-Term 10-Year Comparison of Girls with Congenital Adrenal Hyperplasia Who Underwent Early and Late Feminizing Genitoplasty. Pediatric Surgery International 2023 Jun; 39:222. DOI: Google Scholar
[14]
1007/s00383-023-05498-8 Google Scholar